颞下颌关节色素沉着绒毛结节性滑膜炎的数字化诊疗1例

doi:10.7518/hxkq.2023.2023198

华西口腔医学杂志 ›› 2023, Vol. 41 ›› Issue (6): 725-730.doi: 10.7518/hxkq.2023.2023198

颞下颌关节色素沉着绒毛结节性滑膜炎的数字化诊疗1例

李晨曦¹^,²^,³(), 帕热克江·帕塔尔null¹^,², 龚忠诚¹^,²()

^1.新疆医科大学第一附属医院（附属口腔医院）口腔颌面肿瘤外科，乌鲁木齐 830054
^2.新疆维吾尔自治区口腔医学研究所，乌鲁木齐 830054
^3.华中科技大学同济医学院附属协和医院口腔医学中心，口腔颌面发育与再生湖北省重点实验室，武汉 430022

收稿日期:2023-06-26 修回日期:2023-09-19 出版日期:2023-12-01 发布日期:2023-11-27
通讯作者: 龚忠诚 E-mail:lichenximed@163.com;gump0904@aliyun.com
作者简介:李晨曦，主治医师，博士，E-mail：lichenximed@163.com
基金资助:
国家自然科学基金(82160189);口腔颌面发育与再生湖北省重点实验室开放课题基金(2022kqhm008);新疆维吾尔自治区科研创新项目(XJ2023G174);西安交通大学口腔医院陕西省牙颌疾病临床医学研究中心开放课题(2020YHJ-B01)

Digitalized diagnosis and treatment of pigmented villonodular synovitis of temporomandibular joint: a case report

Li Chenxi¹^,²^,³(), PAREKEJIANG·Pataer ¹^,², Gong Zhongcheng¹^,²()

^1.Dept. of Oral and Maxillofacial Oncology & Surgery, School/Hospital of Stomatology, The First Affiliated Hospital of Xinjiang Medical University, Urumqi 830054, China
^2.Stomatological Research Institute of Xinjiang Uygur Autonomous Region, Urumqi 830054, China
^3.Dept. of Stomatology, Union Hospital, Tongji Medical College, Huazhong University of Science and Technology, Hubei Province Key Laboratory of Oral and Maxillofacial Development and Regeneration, Wuhan 430022, China

Received:2023-06-26 Revised:2023-09-19 Online:2023-12-01 Published:2023-11-27
Contact: Gong Zhongcheng E-mail:lichenximed@163.com;gump0904@aliyun.com
Supported by:
National Natural Science Foundation of China(82160189);Open Project of Hubei Province Key Laboratory of Oral and Maxillofacial Development and Regeneration(2022kqhm008);Xinjiang Postgraduate Scientific Research Innovation Project(XJ2023G174);College of Stomatology, Xi’an Jiaotong University, Clinical Research Center of Shaanxi Province for Dental and Maxillofacial Diseases(2020YHJB01);Correspondence: Gong Zhongcheng, E-mail: gump0904@aliyun.com

摘要/Abstract

摘要：

色素沉着绒毛结节性滑膜炎（PVNS）是一种罕见的局部侵袭性良性肿瘤，极少发生在颞下颌关节（TMJ）。本文报告1例罕见的累及咬肌间隙侵犯颞骨、颧骨及下颌升支的TMJ-PVNS。利用数字化技术确定肿瘤边界并重建正常关节窝，完整切除肿瘤后颞肌筋膜瓣转入钛网与髁突之间固定代替关节盘。术后随访30个月，患者面型对称，张口度43 mm，局部无复发，未出现脑脊液瘘、脑疝等并发症。

关键词: 颞下颌关节, 色素沉着绒毛结节性滑膜炎, 数字化重建, 颞肌筋膜瓣

Abstract:

Pigmented villonodular synovitis (PVNS) is a rare locally aggressive benign tumor in the temporomandibular joint (TMJ). This paper presents a patient with TMJ-PVNS involving masseteric space, temporal bone, zygomatic process, and mandibular ramus. Digital technique was used to determine the boundary of the lesion and reconstruct the normal glenoid fossa. The temporalis myofascial flap was transplanted between titanium mesh and condyle to reconstruct the disk after the complete resection of the tumor. The patient’s facial profile is symmetrical, with a mouth ope-ning of 43 mm. No local recurrence and complications, such as cerebrospinal fluid fistula and encephaloceles, were detected during 30-month follow-up period.

Key words: temporomandibular joint, pigmented villonodular synovitis, digital reconstruction, temporalis myofascial flap

中图分类号:

R 739.8

李晨曦, 帕热克江·帕塔尔null, 龚忠诚. 颞下颌关节色素沉着绒毛结节性滑膜炎的数字化诊疗1例[J]. 华西口腔医学杂志, 2023, 41(6): 725-730.

Li Chenxi, PAREKEJIANG·Pataer , Gong Zhongcheng. Digitalized diagnosis and treatment of pigmented villonodular synovitis of temporomandibular joint: a case report[J]. West China Journal of Stomatology, 2023, 41(6): 725-730.

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颞下颌关节色素沉着绒毛结节性滑膜炎的数字化诊疗1例

Digitalized diagnosis and treatment of pigmented villonodular synovitis of temporomandibular joint: a case report

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