误诊为面部炎症的Rosai-Dorfman病1例

doi:10.7518/hxkq.2024.2023455

华西口腔医学杂志 ›› 2024, Vol. 42 ›› Issue (5): 671-674.doi: 10.7518/hxkq.2024.2023455

误诊为面部炎症的Rosai-Dorfman病1例

陈雅琦(), 马文, 聂根定, 黎明(), 崔庆赢()

昆明医科大学口腔医学院·附属口腔医院口腔颌面外科云南省口腔医学重点实验室，昆明 650106

收稿日期:2023-12-27 修回日期:2024-04-28 出版日期:2024-10-01 发布日期:2024-09-21
通讯作者: 黎明,崔庆赢 E-mail:1804520539@qq.com;1020513890@qq.com;qyingcui@163.com
作者简介:陈雅琦，医师，硕士，E-mail：1804520539@qq.com
基金资助:
云南省口腔疾病临床医学研究中心科研基金(2022YB-002);昆明医科大学教学研究教学改革专题(2022-JY-Y-146);云南省高层次人才培养支持计划(YNWR-MY-2020-086)

One case of Rosai-Dorfman disease misdiagnosed as facial inflammation

Chen Yaqi(), Ma Wen, Nie Gending, Li Ming(), Cui Qingying()

Dept. of Oral and Maxillofacial Surgery, Kunming Medical University School and Hospital of Stomatology; Yunnan Key Laboratory of Stomatology, Kunming 650106, China

Received:2023-12-27 Revised:2024-04-28 Online:2024-10-01 Published:2024-09-21
Contact: Li Ming,Cui Qingying E-mail:1804520539@qq.com;1020513890@qq.com;qyingcui@163.com
Supported by:
Fund of Clinical Medical Research Center of Oral Diseases in Yunnan Province(2022YB002);Fund of Kunming Medical University of Teaching Research Teaching Reform Topic(2022-JY-Y-146);Fund of Yunnan High Level Talent Training Support Plan(YNWR-MY-2020-086)

摘要/Abstract

摘要：

Rosai-Dorfman病是一种罕见的非朗格汉斯细胞组织细胞增生症，其病因及发病机制尚未完全阐明，发生在颌面部更为罕见，本文就1例首诊误诊为口腔疾病造成的面部炎症、终诊断为Rosai-Dorfman病的病例进行报道，结合文献对其临床特点、诊疗及预后进行讨论，为今后诊断和鉴别发生在面颊部的Rosai-Dorfman病提供参考。

关键词: Rosai-Dorfman病, 窦组织细胞增生伴巨大淋巴结病, 颌面部

Abstract:

Rosai-Dorfman disease (RDD) is a rare non-Langerhans cell histiocytosis. The etiology and pathogenesis of RDD have not been fully explained, and its occurrence is even rarer in the maxillofacial region. This paper reported a patient who was first misdiagnosed as facial inflammation caused by oral disease and finally diagnosed as RDD. Clinical features, diagnosis, treatment, and prognosis were discussed based on the literature. This work provides reference for future diagnosis and differentiation of RDD in cheek.

Key words: Rosai-Dorfman disease, sinus histocytosis with massive lymphadenopathy, maxillofacial region

中图分类号:

R739.81

陈雅琦, 马文, 聂根定, 黎明, 崔庆赢. 误诊为面部炎症的Rosai-Dorfman病1例[J]. 华西口腔医学杂志, 2024, 42(5): 671-674.

Chen Yaqi, Ma Wen, Nie Gending, Li Ming, Cui Qingying. One case of Rosai-Dorfman disease misdiagnosed as facial inflammation[J]. West China Journal of Stomatology, 2024, 42(5): 671-674.

图/表 4

参考文献 13

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误诊为面部炎症的Rosai-Dorfman病1例

One case of Rosai-Dorfman disease misdiagnosed as facial inflammation

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